PTCH1 isoform 1b is the major transcript in the development of basal cell nevus syndrome

Robbert-Jan C. A. M. Gielen, Marieke G. H. C. Reinders, Hannele K. Koillinen, Aimee D. C. Paulussen, Klara Mosterd, Michel van Geel*

*Corresponding author for this work

Research output: Contribution to journalArticleAcademicpeer-review

30 Downloads (Pure)

Abstract

Basal cell nevus syndrome (BCNS) is an autosomal dominant disorder most commonly caused by a germline mutation in the PTCH1 gene. PTCH1 is known to have different isoforms with different functional properties and expression patterns among tissues. We detected a novel, pathogenic de novo mutation in PTCH1 isoform 1b (c.114delG) in a BCNS patient. Furthermore, we elucidated the specific expression pattern of PTCH1 isoforms in normal skin, BCC and peripheral blood by studying expression of different PTCH1 isoforms. Human skin showed expression of isoforms 1b and 1d, while peripheral blood additionally showed la and le expression. BCCs showed expression of all isoforms. Here we report a patient with a novel, isoform 1b specific mutation in PTCH1 and thereby distinguish PTCH1 isoform 1b as the major transcript in the development of BCNS.
Original languageEnglish
Pages (from-to)965-969
Number of pages5
JournalJournal of Human Genetics
Volume63
Issue number9
DOIs
Publication statusPublished - 1 Sept 2018

Keywords

  • TUMOR-SUPPRESSOR
  • CARCINOMA SYNDROME
  • 1ST EXONS
  • PROTEIN
  • PATCHED1
  • GENE

Cite this